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Griscelli syndrome (GS) is a rare genetic disorder that is classified into three distinct types. Partial oculocutaneous albinism is common to all three types. In addition, neurological abnormalities and immunodeficiency are seen in types 1 and 2, respectively. Hemophagocytic lymphohistiocytosis (HLH) is common in GS-2. We present a case of a four-year-old boy who presented with features of albinism, recurrent infections, and hepatosplenomegaly. His complete blood count (CBC) revealed pancytopenia, and bone marrow biopsy showed prominent hemophagocytic activity. Serum ferritin was elevated, and fibrinogen was low. The diagnostic criteria for HLH were met. Hair shaft microscopy revealed large, irregularly spaced clumps of melanin in the medulla. A diagnosis of GS-2 was made. Unfortunately, the patient died before mutation analysis could be performed. Along with this case report, we have included a literature review of 42 cases from 33 case reports and case series. We also propose a diagnostic approach to three hematological disorders associated with albinism, Chediak-Higashi syndrome (CHS), Hermansky-Pudlak syndrome (HPS), and GS.
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http://dx.doi.org/10.7759/cureus.86445 | DOI Listing |
Front Immunol
August 2025
Department of Hematology and Medical Oncology, University Medical Center, Johannes Gutenberg University, Mainz, Germany.
Griscelli syndrome type 2 (GS-2) is a rare congenital immune dysfunction characterized by partial albinism and recurrent episodes of hemophagocytic lymphohistiocytosis (HLH). It is caused by a variant in the gene encoding Rab27a leading to a degranulation defect in melanocytes, natural killer (NK)- and T cells. Prognosis of patients with GS-2 is limited by repetitive episodes of life-threatening HLH with onset in early childhood.
View Article and Find Full Text PDFCureus
June 2025
Pathology, University College of Medicine and Dentistry, The University of Lahore, Lahore, PAK.
Griscelli syndrome (GS) is a rare genetic disorder that is classified into three distinct types. Partial oculocutaneous albinism is common to all three types. In addition, neurological abnormalities and immunodeficiency are seen in types 1 and 2, respectively.
View Article and Find Full Text PDFBone Marrow Transplant
July 2025
Pediatric BMT Unit, Acibadem Adana Hospital, Adana, Turkey.
Primary hemophagocytic lymphohistiocytosis (p-HLH) can be cured with allogeneic haematopoietic stem cell transplantation (allo-HSCT). It remains unclear whether HSCT outcomes are affected by the presence of different genetic mutations. We used data obtained from children who underwent allo-HSCT for HLH to examine the effects of genetic mutations on HSCT outcomes.
View Article and Find Full Text PDFJ Cutan Pathol
July 2025
Department of Pediatrics, Government Medical College (GMC), Srinagar, India.
J Dermatol Sci
May 2025
Department of Genetics & Biotechnology, Graduate School of Biotechnology, College of Life Sciences, Kyung Hee University, Yongin, Korea. Electronic address:
Background: Melanophilin is an effector protein that interacts with Rab27a and Myosin Va and regulates melanosome transport in melanocytes. Type 3 Griscelli syndrome, a mutation in Mlph gene, is characterized by partial pigment dilution, without any associated systemic problems. P300 plays roles in histone acetylation and changes chromatin state.
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